Cheng S.-Y.SHYH-JYE CHENHONG-SHIEE LAI2020-07-072020-07-0720161943-0922https://scholars.lib.ntu.edu.tw/handle/123456789/509174Congenital anterior urethrocutaneous fistula and megalourethra are both rare anomalies. These anomalies are commonly associated with other anorectal or genitourinary anomalies and evaluated with voiding cystourethrography. We examined a 34-month-old boy who presented with a fistula at the penoscrotal junction. A voiding cystourethrogram showed a jet of urine coming through the fistula and proximal saccular dilatation of the penile urethra. We present the imaging findings of the first case of an association between a congenital anterior urethrocutaneous fistula at the penoscrotal junction and a proximal penile megalourethra. We also discuss the etiology, management, and differential diagnosis of this entity, and review the literature. ? 2016, EduRad. All rights reserved.[SDGs]SDG3Article; case report; child; congenital anterior urethrocutaneous fistula; human; male; megalourethra; micturition cystourethrography; micturition disorder; penile urethra; physical examination; prepuce; urethra fistula; urine flow rate; urine incontinence; urogenital tract disease; abnormalities; Cutaneous Fistula; diagnostic imaging; differential diagnosis; hypospadias; multiple malformation syndrome; Penile Diseases; preschool child; urethra; Urethral Diseases; Urinary Fistula; Abnormalities, Multiple; Child, Preschool; Cutaneous Fistula; Diagnosis, Differential; Humans; Hypospadias; Male; Penile Diseases; Urethra; Urethral Diseases; Urinary Fistulajournal article10.3941/jrcr.v10i2.2533272001602-s2.0-84959375271